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362121

Immunological profile of patients with skeletal dysplasia and disproportionate short stature

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Last updated: 05 Jan 2025

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Abstract

Introduction
Skeletal dysplasia is a clinically diverse and genetically heterogeneous group of disorders affecting skeletal development among which several phenotypes could be associated with manifestations of immunodeficiency (ID). In many cases, these manifestations may be attributed to the original anatomical and physiological derangement caused by the genetic abnormality, but in other cases, there could be a concurrent primary defect in the immune system. These cases are called to have syndromic ID.
Aim
This study aimed to unravel syndromic ID among cases with skeletal dysplasias and disproportionate short stature and to specify a set of laboratory investigations that could be used as a panel for initial evaluation of suspected cases.
Patients and methods
This is an observational case–control single-center study, in which 25 patients with disproportionate dwarfism owing to skeletal dysplasia, along with 20 healthy participants matched for age and sex, were included. Both patients and controls were categorized into two age groups: from 0 to 3 years and from more than 3 to 15 years.
Results
Results of the study revealed the presence of nine cases of syndromic ID in the studied patients, that is, five in the younger age group (from 0 to 3 years) and four in the older age group (from >3 to 15 years), with a prevalence rate that equals 36% among the studied population.
Conclusion
The present work emphasizes the importance of screening for syndromic IDs in providing proper genetic counseling for patients and optimizing clinical care given by providing early and appropriate treatment. The implementation of flow cytometric measurement of lymphocyte subsets and immunoglobulin (Ig) quantification in cases suspected of having syndromic ID have shown to be useful as an initial panel for immunological evaluation of patients.

DOI

10.4103/mxe.mxe_21_20

Keywords

immune defects, primary immunodeficiency, skeletal dysplasia, syndromic immunodeficiency

Authors

First Name

Raghda M.

Last Name

Ghorab

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First Name

Nahla M.

Last Name

Zakaria

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First Name

Shams M.

Last Name

Kholoussi

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First Name

Rasha M.

Last Name

Mamdouh

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First Name

Haiam A.

Last Name

Raouf

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First Name

Rasha M.

Last Name

Elhossini

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First Name

Doaa M.

Last Name

Abdelaziz

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First Name

Alaaeldin

Last Name

Fayez

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Email

afayez_nrc@yahoo.com

City

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Orcid

0000-0003-3433-3033

First Name

Samia A.

Last Name

Temtamy

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Volume

9

Article Issue

2

Related Issue

48657

Issue Date

2021-05-01

Receive Date

2020-11-02

Publish Date

2021-05-13

Print ISSN

2090-8571

Online ISSN

2090-763X

Link

https://mxe.journals.ekb.eg/article_362121.html

Detail API

https://mxe.journals.ekb.eg/service?article_code=362121

Order

362,121

Publication Type

Journal

Publication Title

Middle East Journal of Medical Genetics

Publication Link

https://mxe.journals.ekb.eg/

MainTitle

Immunological profile of patients with skeletal dysplasia and disproportionate short stature

Details

Type

Article

Created At

29 Dec 2024