Beta
359554

A rare case of bilateral trigeminal palsy presenting as a complication of Sjogren syndrome

Article

Last updated: 05 Jan 2025

Subjects

-

Tags

-

Abstract

Sjogren syndrome is a chronic disorder affecting the exocrine glands of the body, mostly lacrimal and salivary glands, resulting in sicca symptoms. Diagnosis is aided by the presence of anti-Ro and anti-La antibodies and gland biopsy showing lymphocytic infiltration. Bilateral loss of facial sensation in Sjogren syndrome (SS) has not been reported before, although unilateral trigeminal palsy as a presentation of SS has been reported in literature. A 25-year-old lady presented in the neurology clinic with complete facial numbness and vision loss for 1 month. The vision worsened, leading to complete blindness. She had dry mouth and dry eyes for the past 3 months. She was diagnosed with SS using American–European consensus Sjogren criteria. Electrophysiological blink reflex testing confirmed complete trigeminal nerve palsy. SS was treated with prednisolone, 1 mg/kg/day, with a poor response. Symptomatic treatment was given for sicca symptoms, which improved significantly. Corneal transplantation was done for visual loss, but limited improvement was seen.

DOI

10.4103/kamj.kamj_57_16

Keywords

Blink Reflex, complete blindness, corneal transplant, Sjogren syndrome, trigeminal nerve palsy

Authors

First Name

Ali

Last Name

Ilyas

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

Wasim T.

Last Name

Malik

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

Anam

Last Name

Abrar

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

Faleha

Last Name

Zafar

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

Volume

23

Article Issue

1

Related Issue

48350

Issue Date

2017-01-01

Receive Date

2016-11-17

Publish Date

2017-01-01

Print ISSN

1687-4625

Online ISSN

2356-8097

Link

https://kamj.journals.ekb.eg/article_359554.html

Detail API

https://kamj.journals.ekb.eg/service?article_code=359554

Order

359,554

Publication Type

Journal

Publication Title

Kasr Al Ainy Medical Journal

Publication Link

https://kamj.journals.ekb.eg/

MainTitle

A rare case of bilateral trigeminal palsy presenting as a complication of Sjogren syndrome

Details

Type

Article

Created At

29 Dec 2024