Beta
335410

Congenital absence of the skin: a case series report

Article

Last updated: 29 Dec 2024

Subjects

-

Tags

-

Abstract

Background
Extracranial congenital skin defects, defined as aplasia cutis congenita (ACC), are a rare clinical entity. The form of presentation varies among patients according to the causal agent and the point during pregnancy at which the defect occurs. We present a series of cases of noncranial ACC, analysing its possible etiopathogenesis and the evolution of the lesions.
Materials and methods
This is a retrospective review of cases of extracranial ACC at a tertiary hospital.
Case presentation
Patient 1 is a full-term newborn of a monochorionic diamniotic gestation with the death of one foetus at 14 weeks of gestational age. Physical examination revealed two skin defects located on the posterior aspect of both thoraco-abdominal flanks. Patient 2 is a full-term newborn presenting with an ulcer on the nasal tip and cephalic extension on a follow-up pregnancy ultrasound. Patient 3 is a full-term newborn of a monochorionic diamniotic gestation with twin feticide due to encephalocele, presenting an ulcer on the lateral aspect of the proximal third of her right leg. The gestation associates severe oligohydramnios due to premature rupture of the membranes and breech presentation. Patient 4 is a full-term newborn with an ulcer on the left antecubital fossa with no relevant gestational history.
Conclusion
The analysis of the obstetric history and the clinical presentation of the lesions helps to guide the aetiopathogenic diagnosis of congenital skin defects. The increased intracompartment pressure in the limbs is related to the increased severity of skin lesions and musculoskeletal and nerve involvement. Conservative treatment is related to a good prognosis for the lesions.

DOI

10.1186/s43159-022-00166-3

Authors

First Name

Jesús Vicente

Last Name

Redondo Sedano

MiddleName

-

Affiliation

-

Email

jesusredondosedano@gmail.com

City

-

Orcid

0000-0002-8850-7599

First Name

María Dolores

Last Name

Delgado Muñoz

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

Alicia

Last Name

Gómez Sánchez

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

Sara Monserrat

Last Name

Proaño Landazuri

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

María

Last Name

López Maestro

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

Jesús

Last Name

Rodríguez Calvo

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

Cecilia

Last Name

Castellano Yáñez

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

Andrés

Last Name

Gómez Fraile

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

First Name

María Eunate

Last Name

Marti Carrera

MiddleName

-

Affiliation

-

Email

-

City

-

Orcid

-

Volume

18

Article Issue

1

Related Issue

45425

Issue Date

2022-01-01

Receive Date

2022-02-13

Publish Date

2022-05-02

Print ISSN

1687-4137

Online ISSN

2090-5394

Link

https://apsj.journals.ekb.eg/article_335410.html

Detail API

https://apsj.journals.ekb.eg/service?article_code=335410

Order

335,410

Publication Type

Journal

Publication Title

Annals of Pediatric Surgery

Publication Link

https://apsj.journals.ekb.eg/

MainTitle

Congenital absence of the skin: a case series report

Details

Type

Article

Created At

20 Dec 2024